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Case Report

Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review

  • Authors:
    • Ke‑Jie Chang
    • Meng‑Hang Yang
    • Bing Li
    • Hai Huang
  • View Affiliations / Copyright

    Affiliations: Department of Respiratory and Critical Care Medicine, Changzheng Hospital, Second Military Medical University, Shanghai 200003, P.R. China
  • Pages: 3851-3855
    |
    Published online on: March 30, 2020
       https://doi.org/10.3892/etm.2020.8627
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Abstract

Gorham-Stout syndrome (GSS) is a rare disease characterized by spontaneous and progressive osteolysis caused by benign proliferation of lymphatic vessels or capillaries. It most commonly occurs in children or young individuals without any inherited predisposition. GSS most commonly affects the shoulder girdle, pelvis, ribs and skull. Its diagnosis is mainly based on radiological and pathological findings. The present study reports on the case of a 22‑year‑old male patient diagnosed with GSS involving the C1‑T1 vertebrae accompanied by bilateral pleural effusion. Resection of the occipital and cervical vertebral lesions and spinal reconstruction using an internal fixator were successfully performed via the posterior approach. After the surgery, the patient received bisphosphonate treatment and vitamin D supplementation. The pleural effusion gradually decreased. At the 18‑month follow‑up visit, no evidence of new bone obstruction was present and the patient had no neurological sequelae.
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Copy and paste a formatted citation
Spandidos Publications style
Chang KJ, Yang MH, Li B and Huang H: Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review. Exp Ther Med 19: 3851-3855, 2020.
APA
Chang, K., Yang, M., Li, B., & Huang, H. (2020). Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review. Experimental and Therapeutic Medicine, 19, 3851-3855. https://doi.org/10.3892/etm.2020.8627
MLA
Chang, K., Yang, M., Li, B., Huang, H."Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review". Experimental and Therapeutic Medicine 19.6 (2020): 3851-3855.
Chicago
Chang, K., Yang, M., Li, B., Huang, H."Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review". Experimental and Therapeutic Medicine 19, no. 6 (2020): 3851-3855. https://doi.org/10.3892/etm.2020.8627
Copy and paste a formatted citation
x
Spandidos Publications style
Chang KJ, Yang MH, Li B and Huang H: Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review. Exp Ther Med 19: 3851-3855, 2020.
APA
Chang, K., Yang, M., Li, B., & Huang, H. (2020). Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review. Experimental and Therapeutic Medicine, 19, 3851-3855. https://doi.org/10.3892/etm.2020.8627
MLA
Chang, K., Yang, M., Li, B., Huang, H."Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review". Experimental and Therapeutic Medicine 19.6 (2020): 3851-3855.
Chicago
Chang, K., Yang, M., Li, B., Huang, H."Surgical management of Gorham‑Stout syndrome involving the cervical spine with bilateral pleural effusion: A case report and literature review". Experimental and Therapeutic Medicine 19, no. 6 (2020): 3851-3855. https://doi.org/10.3892/etm.2020.8627
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